Pulse Brain · Growing Health Evidence Index
Peer-reviewed

Neonatal Chylothorax and Dysmorphic Phenotype: A Noonan Syndrome?

Sara Suárez-Cabezas, Daniel Natera‐de Benito, Pilar Pérez-Segura, Lucia Llorente-Otones, María José Alcázar Villar, María José Rivero-Martin Mj

Journal of Rare Disorders: Diagnosis & Therapy · 2016

Read source ↗ All evidence

Summary

Congenital chylothorax is an abnormal accumulation of chyle in the pleural space. Most are idiopathic, but it may be a characteristic of Down, Turner and Noonan syndromes. We report the case of a 4 y old female with a history of polyhydramnios, hydrops fetalis and bilateral congenital chylothorax. She had a pulmonary valve stenosis, short stature (<P3), psychomotor delay, and distinctive facial features. Karyotype and cerebral magnetic resonance were normal. She was diagnosed with Noonan syndrome according to Van der Burgt criteria. Molecular genetic studies were undertaken and a p.Glu139Asp mutation was found in PTPN11. This report illustrates that NS should be suspected in patients presenting with congenital chylothorax, dysmorphic phenotype and a normal karyotype. Based on the proportio

Source type
Peer-reviewed study
Catalogue ID
BFmoakvg7x-iws3nc
Pulse AI · ask about this record

Dig deeper with Pulse AI.

Pulse AI has read the whole catalogue. Ask about this record, its theme, or how the findings apply to UK farming and policy — every answer cites the underlying studies.