Pulse Brain · Growing Health Evidence Index
Tier 4 — Narrative / commentaryPeer-reviewed

Neonatal Chylothorax and Dysmorphic Phenotype: A Noonan Syndrome?

Sara Suárez-Cabezas, Daniel Natera‐de Benito, Pilar Pérez-Segura, Lucia Llorente-Otones, María José Alcázar Villar, María José Rivero-Martin Mj

Journal of Rare Disorders: Diagnosis & Therapy · 2016

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Summary

This case report describes a paediatric patient presenting with congenital bilateral chylothorax, growth restriction, psychomotor delay and characteristic facial dysmorphism, subsequently diagnosed with Noonan syndrome. Molecular genetic analysis identified a pathogenic mutation (p.Glu139Asp) in the PTPN11 gene. The report highlights that Noonan syndrome should be considered in the differential diagnosis of congenital chylothorax accompanied by dysmorphic features and normal karyotype.

UK applicability

The findings are applicable to UK paediatric clinical practice insofar as they reinforce diagnostic criteria for rare genetic syndromes; however, as a single case report, the evidence base is limited for influencing clinical guidelines or policy without corroborating studies.

Key measures

Clinical phenotype assessment; karyotype analysis; cerebral MRI findings; PTPN11 gene sequencing; Van der Burgt diagnostic criteria for Noonan syndrome

Outcomes reported

Case report of a 4-year-old female with congenital chylothorax, dysmorphic features, and pulmonary valve stenosis diagnosed with Noonan syndrome; identification of p.Glu139Asp mutation in PTPN11 gene.

Theme
Nutrition & health
Subject
Maternal, infant & child nutrition
Study type
Commentary
Study design
Case report
Source type
Peer-reviewed study
Status
Published
Geography
Spain
System type
Human clinical
Catalogue ID
BFmoc27lzg-u2n2im

Topic tags

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