Pulse Brain · Growing Health Evidence Index
Tier 4 — Narrative / commentaryPeer-reviewed

Neonatal Chylothorax and Dysmorphic Phenotype: A Noonan Syndrome?

Sara Suárez-Cabezas, Daniel Natera‐de Benito, Pilar Pérez-Segura, Lucia Llorente-Otones, María José Alcázar Villar, María José Rivero-Martin Mj

Journal of Rare Disorders: Diagnosis & Therapy · 2016

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Summary

This case report describes a paediatric patient with congenital chylothorax and dysmorphic phenotype diagnosed with Noonan syndrome, confirmed by PTPN11 gene mutation. The authors emphasise that Noonan syndrome should be considered in the differential diagnosis of neonatal chylothorax with normal karyotype, as genetic syndromes may underlie cases previously classified as idiopathic. The finding illustrates the utility of molecular genetic testing in clarifying syndromic presentations of rare congenital conditions.

UK applicability

The case report is relevant to UK paediatric practice and genetic diagnostic pathways, offering clinicians guidance on recognising syndromic causes of congenital chylothorax. Results may inform screening protocols in UK neonatal units, though applicability depends on adoption of molecular testing protocols in routine clinical care.

Key measures

Clinical phenotype (facial features, short stature, psychomotor delay, pulmonary valve stenosis), chylothorax presentation, karyotype analysis, cerebral magnetic resonance imaging, PTPN11 gene sequencing

Outcomes reported

The study reported a case of a 4-year-old female presenting with congenital bilateral chylothorax, dysmorphic features, and pulmonary valve stenosis, subsequently diagnosed with Noonan syndrome. Molecular genetic analysis identified a p.Glu139Asp mutation in PTPN11 gene.

Theme
Nutrition & health
Subject
Maternal, infant & child nutrition
Study type
Commentary
Study design
Case report
Source type
Peer-reviewed study
Status
Published
System type
Human clinical
Catalogue ID
BFmohg5dye-t3y8or

Topic tags

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